Upper Dysphagia Revealing Diffuse Idiopathic Skeletal Hyperostosis (Forestier's Disease): A Case Report and Review of the Literature

Authors

  • Abdallah Witti Adou 1. Medical-surgical Center of the National Police, Djibouti
  • Hassan Mohamed Bourhan 1. Medical-surgical Center of the National Police, Djibouti
  • Abdou SY 2. ENT Department, Children’s Hospital of Diamniadio, Dakar, Senegal.
  • Mohamed Osman Guelleh 3. Hôpital Militaire, Djibouti
  • Abdi Okhier Kamil 3. Hôpital Militaire, Djibouti
  • Saredo Aganeh Osman 1. Medical-surgical Center of the National Police, Djibouti
  • Kamil Ahmed Kamil 1. Medical-surgical Center of the National Police, Djibouti
  • Birame Loum 4. Service d’ORL et de Chirurgie Cervico-Faciale, Hôpital Principal de Dakar, Sénégal

DOI:

https://doi.org/10.5281/hra.v2i4.5470

Keywords:

la maladie de forestier, dysphagie, hyperostose squelettique idiopathique, DISH

Abstract

ABSTRACT
Diffuse idiopathic skeletal hyperostosis (DISH) or Forestier's disease is a benign condition characterized by ossification of the ligaments which mainly involves the anterior longitudinal ligament and less frequently the posterior longitudinal part of the spines. We report a case of Forestier's disease revealed by dysphagia to solids in a 62-year-old patient with no particular pathological history, received in our department for progressively worsening solids dysphagia evolving for approximately more than 10 years, with no other associated signs, with a tendency to become complete for one month. The cervical computed tomography (CT) performed revealed an anterior exostosis at the level of C4-C5, anterior marginal osteophytosis, evoking Forestier's disease. The patient underwent complete excision of the osteophytes located at the level of C4-C5 by way of anterolateral cervicotomy. After a follow-up of 09 months postoperatively, the patient was doing well and the cervical CT performed after 03 months postoperatively showed a complete disappearance of the osteophytes. In conclusion, Forestier's disease, although rare, can present with symptoms such as dysphagia and should be considered in the differential diagnosis of patients with progressive difficulty swallowing. Early diagnosis and appropriate management, such as surgical excision of the osteophytes, can lead to a favorable outcome and improvement in symptoms. Regular follow-up is essential to monitor the progression of the disease and ensure optimal patient care.
RÉSUMÉ
La maladie diffuse de l'hyperostose squelettique idiopathique (DISH) ou maladie de Forestier est une affection bénigne caractérisée par l'ossification des ligaments qui touche principalement le ligament longitudinal antérieur et plus rarement la partie postérieure des vertèbres. Nous rapportons un cas de maladie de Forestier révélé par une dysphagie aux solides chez un patient de 62 ans sans antécédents pathologiques particuliers, admis dans notre service pour une dysphagie aux solides progressivement aggravée évoluant depuis plus de 10 ans, sans autres signes associés, tendant à devenir complète depuis un mois. La tomodensitométrie (TDM) cervicale réalisée a révélé une exostose antérieure au niveau de C4-C5, une ostéophytose marginale antérieure, évoquant la maladie de Forestier. Le patient a subi une exérèse complète des ostéophytes situés au niveau de C4-C5 par cervicotomie antérolatérale. Après un suivi de 09 mois postopératoire, le patient se portait bien et la TDM cervicale réalisée après 03 mois postopératoire a montré une disparition complète des ostéophytes. En conclusion, la maladie de Forestier, bien que rare, peut se manifester par des symptômes tels que la dysphagie et doit être envisagée dans le diagnostic différentiel des patients présentant une difficulté progressive à avaler. Un diagnostic précoce et une prise en charge appropriée, telle que l'exérèse chirurgicale des ostéophytes, peuvent entraîner un pronostic favorable et une amélioration des symptômes. Un suivi régulier est essentiel pour surveiller l'évolution de la maladie et assurer des soins optimaux au patient.

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Published

28-03-2024

How to Cite

Abdallah Witti Adou, Hassan Mohamed Bourhan, Abdou SY, Mohamed Osman Guelleh, Abdi Okhier Kamil, Saredo Aganeh Osman, Kamil Ahmed Kamil, & Birame Loum. (2024). Upper Dysphagia Revealing Diffuse Idiopathic Skeletal Hyperostosis (Forestier’s Disease): A Case Report and Review of the Literature. HEALTH RESEARCH IN AFRICA, 2(4). https://doi.org/10.5281/hra.v2i4.5470

Issue

Vol. 2 No. 4 (2024): Health Research in Africa

Section

Case Reports

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